Abstract
Adamantinoma is an extremely rare tumour originating from bone that can be divided
into classical and osteofibrous dysplasia (OFD)-like adamantinoma. This low-grade
malignancy almost exclusively occurs in long bones, and only few cases of mandibular
adamantinoma have been reported. Here, we report the case of a 30-year-old female
with a 2-year history of right mandible tenderness. Radiological examinations showed
a lytic lesion involving the right mandible without a well-defined margin. Biopsy
confirmed the diagnosis of adamantinoma. She underwent a segmental mandibulectomy
and reconstruction with a fibula flap. The definitive diagnosis was OFD-like adamantinoma.
However, the tumour recurred after 5 years. The residual mandible and fibula flap
were widely involved. A total mandibulectomy was performed. Five years later, there
is no evidence of recurrence or metastasis. We recommend that adamantinoma be treated
by radical resection with clear margins, and long-term surveillance is necessary due
to the likely high local recurrence rate and the potential for late tumour metastasis.
Key words
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Article info
Publication history
Published online: December 06, 2020
Accepted:
October 9,
2020
Identification
Copyright
© 2020 Published by Elsevier Ltd on behalf of International Association of Oral and Maxillofacial Surgeons.
